U.S. flag

An official website of the United States government

Format

Send to:

Choose Destination

Microphthalmia-brain atrophy syndrome(MOBA; MCOPS10)

MedGen UID:
370809
Concept ID:
C1970013
Disease or Syndrome
Synonyms: Microphthalmia and brain atrophy; Microphthalmia syndromic 10
SNOMED CT: Microphthalmia with brain atrophy syndrome (720010009); Syndromic microphthalmia type 10 (720010009)
Modes of inheritance:
Autosomal recessive inheritance
MedGen UID:
141025
Concept ID:
C0441748
Intellectual Product
Source: Orphanet
A mode of inheritance that is observed for traits related to a gene encoded on one of the autosomes (i.e., the human chromosomes 1-22) in which a trait manifests in individuals with two pathogenic alleles, either homozygotes (two copies of the same mutant allele) or compound heterozygotes (whereby each copy of a gene has a distinct mutant allele).
 
Monarch Initiative: MONDO:0012638
OMIM®: 611222
Orphanet: ORPHA77299

Definition

Syndrome with characteristics of congenital microphthalmia and blindness, progressive spasticity, microcephaly, seizures and profound intellectual deficit. It has been reported in three children from three unrelated families. While imaging at birth is normal, follow-up studies show progressive atrophy involving the cerebral white matter and cortex, cerebellum, brainstem, and corpus callosum. The white matter changes extend into the subcortical region, leaving only small islands of remaining cortical tissue. [from SNOMEDCT_US]

Term Hierarchy

CClinical test,  RResearch test,  OOMIM,  GGeneReviews,  VClinVar  
  • CROGVMicrophthalmia-brain atrophy syndrome
Follow this link to review classifications for Microphthalmia-brain atrophy syndrome in Orphanet.

Professional guidelines

PubMed

Kirk B, Zanker J, Duque G
J Cachexia Sarcopenia Muscle 2020 Jun;11(3):609-618. Epub 2020 Mar 22 doi: 10.1002/jcsm.12567. PMID: 32202056Free PMC Article
Larson ST, Wilbur J
Am Fam Physician 2020 Jan 15;101(2):95-108. PMID: 31939642
Batsis JA, Villareal DT
Nat Rev Endocrinol 2018 Sep;14(9):513-537. doi: 10.1038/s41574-018-0062-9. PMID: 30065268Free PMC Article

Recent clinical studies

Etiology

Filippini M, Porcari I, Ruffolo AF, Casiraghi A, Farinelli M, Uccella S, Franchi M, Candiani M, Salvatore S
J Sex Med 2022 Mar;19(3):452-470. Epub 2022 Jan 29 doi: 10.1016/j.jsxm.2021.12.010. PMID: 35101378
Kamada T, Maruyama Y, Monobe Y, Haruma K
Dig Endosc 2022 May;34(4):700-713. Epub 2021 Nov 10 doi: 10.1111/den.14175. PMID: 34674318
Wiedmer P, Jung T, Castro JP, Pomatto LCD, Sun PY, Davies KJA, Grune T
Ageing Res Rev 2021 Jan;65:101200. Epub 2020 Oct 29 doi: 10.1016/j.arr.2020.101200. PMID: 33130247
Sanford AM, Morley JE, Berg-Weger M, Lundy J, Little MO, Leonard K, Malmstrom TK
PLoS One 2020;15(6):e0233857. Epub 2020 Jun 5 doi: 10.1371/journal.pone.0233857. PMID: 32502177Free PMC Article
Kirk B, Zanker J, Duque G
J Cachexia Sarcopenia Muscle 2020 Jun;11(3):609-618. Epub 2020 Mar 22 doi: 10.1002/jcsm.12567. PMID: 32202056Free PMC Article

Diagnosis

Cox S, Nasseri R, Rubin RS, Santiago-Lastra Y
Med Clin North Am 2023 Mar;107(2):357-369. doi: 10.1016/j.mcna.2022.10.017. PMID: 36759102
Filippini M, Porcari I, Ruffolo AF, Casiraghi A, Farinelli M, Uccella S, Franchi M, Candiani M, Salvatore S
J Sex Med 2022 Mar;19(3):452-470. Epub 2022 Jan 29 doi: 10.1016/j.jsxm.2021.12.010. PMID: 35101378
The NAMS 2020 GSM Position Statement Editorial Panel
Menopause 2020 Sep;27(9):976-992. doi: 10.1097/GME.0000000000001609. PMID: 32852449
Sanford AM, Morley JE, Berg-Weger M, Lundy J, Little MO, Leonard K, Malmstrom TK
PLoS One 2020;15(6):e0233857. Epub 2020 Jun 5 doi: 10.1371/journal.pone.0233857. PMID: 32502177Free PMC Article
Holden SK, Bettcher BM, Pelak VS
Curr Opin Neurol 2020 Feb;33(1):68-73. doi: 10.1097/WCO.0000000000000767. PMID: 31688098Free PMC Article

Therapy

Groeneweg S, van Geest FS, Peeters RP, Heuer H, Visser WE
Endocr Rev 2020 Apr 1;41(2) doi: 10.1210/endrev/bnz008. PMID: 31754699
Scavello I, Maseroli E, Di Stasi V, Vignozzi L
Medicina (Kaunas) 2019 Sep 2;55(9) doi: 10.3390/medicina55090559. PMID: 31480774Free PMC Article
Tournadre A, Vial G, Capel F, Soubrier M, Boirie Y
Joint Bone Spine 2019 May;86(3):309-314. Epub 2018 Aug 8 doi: 10.1016/j.jbspin.2018.08.001. PMID: 30098424
Landi F, Marzetti E, Martone AM, Bernabei R, Onder G
Curr Opin Clin Nutr Metab Care 2014 Jan;17(1):25-31. doi: 10.1097/MCO.0000000000000018. PMID: 24310054
Fearon K, Strasser F, Anker SD, Bosaeus I, Bruera E, Fainsinger RL, Jatoi A, Loprinzi C, MacDonald N, Mantovani G, Davis M, Muscaritoli M, Ottery F, Radbruch L, Ravasco P, Walsh D, Wilcock A, Kaasa S, Baracos VE
Lancet Oncol 2011 May;12(5):489-95. Epub 2011 Feb 4 doi: 10.1016/S1470-2045(10)70218-7. PMID: 21296615

Prognosis

Nishikawa H, Fukunishi S, Asai A, Yokohama K, Nishiguchi S, Higuchi K
Int J Mol Med 2021 Aug;48(2) Epub 2021 Jun 29 doi: 10.3892/ijmm.2021.4989. PMID: 34184088
Holden SK, Bettcher BM, Pelak VS
Curr Opin Neurol 2020 Feb;33(1):68-73. doi: 10.1097/WCO.0000000000000767. PMID: 31688098Free PMC Article
Nascimento CM, Ingles M, Salvador-Pascual A, Cominetti MR, Gomez-Cabrera MC, Viña J
Free Radic Biol Med 2019 Feb 20;132:42-49. Epub 2018 Aug 31 doi: 10.1016/j.freeradbiomed.2018.08.035. PMID: 30176345
Batsis JA, Villareal DT
Nat Rev Endocrinol 2018 Sep;14(9):513-537. doi: 10.1038/s41574-018-0062-9. PMID: 30065268Free PMC Article
Finsterer J, Carvalho EHT
Can J Neurol Sci 2017 Nov;44(6):654-663. doi: 10.1017/cjn.2017.211. PMID: 29391077

Clinical prediction guides

Dowling P, Gargan S, Swandulla D, Ohlendieck K
Int J Mol Sci 2023 Jan 26;24(3) doi: 10.3390/ijms24032415. PMID: 36768735Free PMC Article
Filippini M, Porcari I, Ruffolo AF, Casiraghi A, Farinelli M, Uccella S, Franchi M, Candiani M, Salvatore S
J Sex Med 2022 Mar;19(3):452-470. Epub 2022 Jan 29 doi: 10.1016/j.jsxm.2021.12.010. PMID: 35101378
Li W, Yue T, Liu Y
Biomed Pharmacother 2020 Nov;131:110721. Epub 2020 Sep 10 doi: 10.1016/j.biopha.2020.110721. PMID: 32920517
Kirk B, Zanker J, Duque G
J Cachexia Sarcopenia Muscle 2020 Jun;11(3):609-618. Epub 2020 Mar 22 doi: 10.1002/jcsm.12567. PMID: 32202056Free PMC Article
Nascimento CM, Ingles M, Salvador-Pascual A, Cominetti MR, Gomez-Cabrera MC, Viña J
Free Radic Biol Med 2019 Feb 20;132:42-49. Epub 2018 Aug 31 doi: 10.1016/j.freeradbiomed.2018.08.035. PMID: 30176345

Recent systematic reviews

de Muijnck C, Brink JBT, Bergen AA, Boon CJF, van Genderen MM
Surv Ophthalmol 2023 Jul-Aug;68(4):641-654. Epub 2023 Feb 9 doi: 10.1016/j.survophthal.2023.01.012. PMID: 36764396
Huang CY, Mayer PK, Wu MY, Liu DH, Wu PC, Yen HR
Ageing Res Rev 2022 Dec;82:101747. Epub 2022 Oct 9 doi: 10.1016/j.arr.2022.101747. PMID: 36223875
Freitas DA, Souza-Santos R, Carvalho LMA, Barros WB, Neves LM, Brasil P, Wakimoto MD
PLoS One 2020;15(12):e0242367. Epub 2020 Dec 15 doi: 10.1371/journal.pone.0242367. PMID: 33320867Free PMC Article
Hill DA, Crider M, Hill SR
Am Fam Physician 2016 Dec 1;94(11):884-889. PMID: 27929271
Terelak-Borys B, Skonieczna K, Grabska-Liberek I
Med Sci Monit 2012 Aug;18(8):RA138-144. doi: 10.12659/msm.883260. PMID: 22847215Free PMC Article

Supplemental Content

Table of contents

    Clinical resources

    Practice guidelines

    • PubMed
      See practice and clinical guidelines in PubMed. The search results may include broader topics and may not capture all published guidelines. See the FAQ for details.
    • Bookshelf
      See practice and clinical guidelines in NCBI Bookshelf. The search results may include broader topics and may not capture all published guidelines. See the FAQ for details.

    Recent activity

    Your browsing activity is empty.

    Activity recording is turned off.

    Turn recording back on

    See more...