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Monosomy 9q22.3

MedGen UID:
777998
Concept ID:
C3711390
Disease or Syndrome
Synonym: 9q22.3 microdeletion
SNOMED CT: Monosomy 9q22.3 syndrome (724098008); Microdeletion 9q22.3 (724098008); Monosomy 9q22.3 (724098008); 9q22.3 deletion syndrome (724098008)
Modes of inheritance:
Unknown inheritance
MedGen UID:
989040
Concept ID:
CN307042
Finding
Source: Orphanet
Hereditary clinical entity whose mode of inheritance is unknown.
Not genetically inherited
MedGen UID:
988794
Concept ID:
CN307044
Finding
Source: Orphanet
clinical entity without genetic inheritance.
 
Monarch Initiative: MONDO:0019179
Orphanet: ORPHA77301

Definition

About 20 percent of people with a 9q22.3 microdeletion experience overgrowth (macrosomia), which results in increased height and weight compared to unaffected peers. The macrosomia often begins before birth and continues into childhood. Other physical changes that are sometimes associated with a 9q22.3 microdeletion include the premature fusion of certain bones in the skull (metopic craniosynostosis) and a buildup of fluid in the brain (hydrocephalus). Affected individuals can also have distinctive facial features such as a prominent forehead with vertical skin creases, upward- or downward-slanting eyes, a short nose, and a long space between the nose and upper lip (philtrum).

Many individuals with a 9q22.3 microdeletion have delayed development, particularly affecting the development of motor skills such as sitting, standing, and walking. In some people, the delays are temporary and improve in childhood. More severely affected individuals have permanent developmental disabilities along with intellectual impairment and learning problems. Rarely, seizures have been reported in people with a 9q22.3 microdeletion.

9q22.3 microdeletions also cause the characteristic features of Gorlin syndrome (also known as nevoid basal cell carcinoma syndrome). This genetic condition affects many areas of the body and increases the risk of developing various cancerous and noncancerous tumors. In people with Gorlin syndrome, the type of cancer diagnosed most often is basal cell carcinoma, which is the most common form of skin cancer. Most people with this condition also develop noncancerous (benign) tumors of the jaw, called keratocystic odontogenic tumors, which can cause facial swelling and tooth displacement. Other types of tumors that occur in some people with Gorlin syndrome include a form of childhood brain cancer called a medulloblastoma and a type of benign tumor called a fibroma that occurs in the heart or in a woman's ovaries. Other features of Gorlin syndrome include small depressions (pits) in the skin of the palms of the hands and soles of the feet; an unusually large head size (macrocephaly) with a prominent forehead; and skeletal abnormalities involving the spine, ribs, or skull.

9q22.3 microdeletion is a chromosomal change in which a small piece of chromosome 9 is deleted in each cell. The deletion occurs on the long (q) arm of the chromosome in a region designated q22.3. This chromosomal change is associated with delayed development, intellectual disability, certain physical abnormalities, and the characteristic features of a genetic condition called Gorlin syndrome. [from MedlinePlus Genetics]

Term Hierarchy

CClinical test,  RResearch test,  OOMIM,  GGeneReviews,  VClinVar  
  • CROGVMonosomy 9q22.3

Professional guidelines

PubMed

Zhou Y, Quan Y, Wu Y, Zhang Y
J Int Med Res 2022 Sep;50(9):3000605221121955. doi: 10.1177/03000605221121955. PMID: 36113068Free PMC Article

Recent clinical studies

Etiology

Stark Z, Behrsin J, Burgess T, Ritchie A, Yeung A, Tan TY, Brown NJ, Savarirayan R, Patel N
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Diagnosis

Zhou Y, Quan Y, Wu Y, Zhang Y
J Int Med Res 2022 Sep;50(9):3000605221121955. doi: 10.1177/03000605221121955. PMID: 36113068Free PMC Article
Reichert SC, Zelley K, Nichols KE, Eberhard M, Zackai EH, Martinez-Poyer J
Am J Med Genet A 2015 Apr;167A(4):862-5. Epub 2015 Feb 23 doi: 10.1002/ajmg.a.37013. PMID: 25706929
Muller EA, Aradhya S, Atkin JF, Carmany EP, Elliott AM, Chudley AE, Clark RD, Everman DB, Garner S, Hall BD, Herman GE, Kivuva E, Ramanathan S, Stevenson DA, Stockton DW, Hudgins L
Am J Med Genet A 2012 Feb;158A(2):391-9. Epub 2011 Dec 21 doi: 10.1002/ajmg.a.34216. PMID: 22190277
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Hum Genet 2008 Aug;124(1):1-17. Epub 2008 May 30 doi: 10.1007/s00439-008-0513-9. PMID: 18512078

Prognosis

Garavelli L, Piemontese MR, Cavazza A, Rosato S, Wischmeijer A, Gelmini C, Albertini E, Albertini G, Forzano F, Franchi F, Carella M, Zelante L, Superti-Furga A
Am J Med Genet A 2013 Nov;161A(11):2894-901. Epub 2013 Oct 7 doi: 10.1002/ajmg.a.36259. PMID: 24124115
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Clinical prediction guides

Reichert SC, Zelley K, Nichols KE, Eberhard M, Zackai EH, Martinez-Poyer J
Am J Med Genet A 2015 Apr;167A(4):862-5. Epub 2015 Feb 23 doi: 10.1002/ajmg.a.37013. PMID: 25706929
Muller EA, Aradhya S, Atkin JF, Carmany EP, Elliott AM, Chudley AE, Clark RD, Everman DB, Garner S, Hall BD, Herman GE, Kivuva E, Ramanathan S, Stevenson DA, Stockton DW, Hudgins L
Am J Med Genet A 2012 Feb;158A(2):391-9. Epub 2011 Dec 21 doi: 10.1002/ajmg.a.34216. PMID: 22190277
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