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Susceptibility to angioedema induced by ACE inhibitors(AEACEI)

MedGen UID:
813041
Concept ID:
C3806711
Finding
Synonyms: AEACEI; ANGIOEDEMA INDUCED BY ACE INHIBITORS, SUSCEPTIBILITY TO
 
Gene (location): XPNPEP2 (Xq26.1)
 
Monarch Initiative: MONDO:0100003
OMIM®: 300909

Definition

Approximately 40 million people take ACE inhibitors (ACEi) to treat hypertension and cardiovascular disease. A small proportion of white patients who take ACEi (0.1-0.7%) develop angioedema (AEACEI) (Israili and Hall, 1992; Vleeming et al., 1998), a potentially life-threatening side effect characterized by swelling of the face, lips, tongue, and airway that can lead to suffocation and death if severe. ACEi-associated angioedema is 4 to 5 times more prevalent among African Americans (Brown et al., 1996; Coats, 2002). Other risk factors include female sex, smoking, immunosuppressant therapy, and seasonal allergies. The pathophysiology of ACEi-associated angioedema is thought to be related to increased circulating bradykinin, which is normally degraded by ACE. During pharmacologic ACE inhibition, bradykinin is primarily degraded by aminopeptidase P (summary by Duan et al., 2005 and Woodard-Grice et al., 2010). Aminopeptidase P is encoded by 3 genes: XPNPEP1 (602443) on chromosome 10q25, XPNPEP2 (300145) on chromosome Xq25, and XPNPEP3 (613553) on chromosome 22q13. [from OMIM]

Clinical features

From HPO
Angioedema
MedGen UID:
1543
Concept ID:
C0002994
Pathologic Function
Rapid swelling (edema) of the dermis, subcutaneous tissue, mucosa and submucosal tissues of the skin of the face, normally around the mouth, and the mucosa of the mouth and/or throat, as well as the tongue during a period of minutes to several hours. The swelling can also occur elsewhere, typically in the hands. Angioedema is similar to urticaria, but the swelling is subcutaneous rather than on the epidermis.

Professional guidelines

PubMed

Ali HA, Lomholt AF, Mahmoudpour SH, Hermanrud T, Bygum A, von Buchwald C, Jakobsen MA, Rasmussen ER
PLoS One 2019;14(11):e0224858. Epub 2019 Nov 11 doi: 10.1371/journal.pone.0224858. PMID: 31710633Free PMC Article

Recent clinical studies

Etiology

Mathey CM, Maj C, Eriksson N, Krebs K, Westmeier J, David FS, Koromina M, Scheer AB, Szabo N, Wedi B, Wieczorek D, Amann PM, Löffler H, Koch L, Schöffl C, Dickel H, Ganjuur N, Hornung T, Buhl T, Greve J, Wurpts G, Aygören-Pürsün E, Steffens M, Herms S, Heilmann-Heimbach S, Hoffmann P, Schmidt B, Mavarani L, Andresen T, Sørensen SB, Andersen V, Vogel U, Landén M, Bulik CM; Estonian Biobank Research Team; DBDS Genomic Consortium, Bygum A, Magnusson PKE, von Buchwald C, Hallberg P, Rye Ostrowski S, Sørensen E, Pedersen OB, Ullum H, Erikstrup C, Bundgaard H, Milani L, Rasmussen ER, Wadelius M, Ghouse J, Sachs B, Nöthen MM, Forstner AJ
J Allergy Clin Immunol 2024 Apr;153(4):1073-1082. Epub 2024 Jan 31 doi: 10.1016/j.jaci.2023.11.921. PMID: 38300190
Ghouse J, Ahlberg G, Andreasen L, Banasik K, Brunak S, Schwinn M, Larsen IH, Petersen O, Sørensen E, Ullum H, Rasmussen ER, Eriksson N, Hallberg P, Wadelius M, Bundgaard H, Olesen MS
J Am Coll Cardiol 2021 Aug 17;78(7):696-709. doi: 10.1016/j.jacc.2021.05.054. PMID: 34384552
Ali HA, Lomholt AF, Mahmoudpour SH, Hermanrud T, Bygum A, von Buchwald C, Jakobsen MA, Rasmussen ER
PLoS One 2019;14(11):e0224858. Epub 2019 Nov 11 doi: 10.1371/journal.pone.0224858. PMID: 31710633Free PMC Article
Scott SI, Andersen MF, Aagaard L, Buchwald CV, Rasmussen ER
Curr Diabetes Rev 2018;14(4):327-333. doi: 10.2174/1573399813666170214113856. PMID: 28201967
Wu MA, Perego F, Zanichelli A, Cicardi M
Clin Rev Allergy Immunol 2016 Oct;51(2):162-9. doi: 10.1007/s12016-016-8541-z. PMID: 27113957

Diagnosis

Wu MA, Perego F, Zanichelli A, Cicardi M
Clin Rev Allergy Immunol 2016 Oct;51(2):162-9. doi: 10.1007/s12016-016-8541-z. PMID: 27113957
De Knop KJ, Hagendorens MM, Stevens WJ, De Clerck LS, Ebo DG
Acta Clin Belg 2009 Nov-Dec;64(6):520-8. doi: 10.1179/acb.2009.089. PMID: 20101876
Beltrami L, Zingale LC, Carugo S, Cicardi M
Expert Opin Drug Saf 2006 Sep;5(5):643-9. doi: 10.1517/14740338.5.5.643. PMID: 16907654
Tan EK, Grattan CE
Expert Opin Drug Saf 2004 Sep;3(5):471-84. doi: 10.1517/14740338.3.5.471. PMID: 15335302

Therapy

Mathey CM, Maj C, Eriksson N, Krebs K, Westmeier J, David FS, Koromina M, Scheer AB, Szabo N, Wedi B, Wieczorek D, Amann PM, Löffler H, Koch L, Schöffl C, Dickel H, Ganjuur N, Hornung T, Buhl T, Greve J, Wurpts G, Aygören-Pürsün E, Steffens M, Herms S, Heilmann-Heimbach S, Hoffmann P, Schmidt B, Mavarani L, Andresen T, Sørensen SB, Andersen V, Vogel U, Landén M, Bulik CM; Estonian Biobank Research Team; DBDS Genomic Consortium, Bygum A, Magnusson PKE, von Buchwald C, Hallberg P, Rye Ostrowski S, Sørensen E, Pedersen OB, Ullum H, Erikstrup C, Bundgaard H, Milani L, Rasmussen ER, Wadelius M, Ghouse J, Sachs B, Nöthen MM, Forstner AJ
J Allergy Clin Immunol 2024 Apr;153(4):1073-1082. Epub 2024 Jan 31 doi: 10.1016/j.jaci.2023.11.921. PMID: 38300190
Ali HA, Lomholt AF, Mahmoudpour SH, Hermanrud T, Bygum A, von Buchwald C, Jakobsen MA, Rasmussen ER
PLoS One 2019;14(11):e0224858. Epub 2019 Nov 11 doi: 10.1371/journal.pone.0224858. PMID: 31710633Free PMC Article
Scott SI, Andersen MF, Aagaard L, Buchwald CV, Rasmussen ER
Curr Diabetes Rev 2018;14(4):327-333. doi: 10.2174/1573399813666170214113856. PMID: 28201967
Byrd JB, Adam A, Brown NJ
Immunol Allergy Clin North Am 2006 Nov;26(4):725-37. doi: 10.1016/j.iac.2006.08.001. PMID: 17085287
Tan EK, Grattan CE
Expert Opin Drug Saf 2004 Sep;3(5):471-84. doi: 10.1517/14740338.3.5.471. PMID: 15335302

Prognosis

Maroteau C, Siddiqui MK, Veluchamy A, Carr F, White M, Cassidy AJ, Baranova EV, Rasmussen ER, Eriksson N, Bloch KM, Brown NJ, Bygum A, Hallberg P, Karawajczyk M, Magnusson PKE, Yue QY, Syvänen AC, von Buchwald C, Alfirevic A, Maitland-van der Zee AH, Wadelius M, Palmer CNA; PREDICTION-ADR
Clin Pharmacol Ther 2020 Dec;108(6):1195-1202. Epub 2020 Jul 18 doi: 10.1002/cpt.1927. PMID: 32496628Free PMC Article
Scott SI, Andersen MF, Aagaard L, Buchwald CV, Rasmussen ER
Curr Diabetes Rev 2018;14(4):327-333. doi: 10.2174/1573399813666170214113856. PMID: 28201967

Clinical prediction guides

Maroteau C, Siddiqui MK, Veluchamy A, Carr F, White M, Cassidy AJ, Baranova EV, Rasmussen ER, Eriksson N, Bloch KM, Brown NJ, Bygum A, Hallberg P, Karawajczyk M, Magnusson PKE, Yue QY, Syvänen AC, von Buchwald C, Alfirevic A, Maitland-van der Zee AH, Wadelius M, Palmer CNA; PREDICTION-ADR
Clin Pharmacol Ther 2020 Dec;108(6):1195-1202. Epub 2020 Jul 18 doi: 10.1002/cpt.1927. PMID: 32496628Free PMC Article
Ali HA, Lomholt AF, Mahmoudpour SH, Hermanrud T, Bygum A, von Buchwald C, Jakobsen MA, Rasmussen ER
PLoS One 2019;14(11):e0224858. Epub 2019 Nov 11 doi: 10.1371/journal.pone.0224858. PMID: 31710633Free PMC Article

Recent systematic reviews

Ali HA, Lomholt AF, Mahmoudpour SH, Hermanrud T, Bygum A, von Buchwald C, Jakobsen MA, Rasmussen ER
PLoS One 2019;14(11):e0224858. Epub 2019 Nov 11 doi: 10.1371/journal.pone.0224858. PMID: 31710633Free PMC Article

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