A second decorin frame shift mutation in a family with congenital stromal corneal dystrophy

Am J Ophthalmol. 2006 Sep;142(3):520-1. doi: 10.1016/j.ajo.2006.03.064.

Abstract

Purpose: To identify the genetic defect in a Belgian family with congenital stromal corneal dystrophy.

Design: Case report and result of deoxyribonucleic acid (DNA) analyses.

Methods: DNA sequencing of polymerase chain reaction (PCR) products generated from amplification of exons and adjacent introns of the decorin gene.

Results: The family consisted of a mother and her son, both suffering from congenital stromal corneal dystrophy. In both individuals, a single base pair deletion (c.941delC) in the coding sequence of the decorin gene was demonstrated, predicting a C-terminal truncation of the decorin protein (p.Pro314fsX14).

Conclusion: This is the second family with congenital stromal corneal dystrophy of the cornea in which a frame shift mutation in the decorin gene has been detected. Both in this family and in a previously reported Norwegian family, a decorin protein missing the 33 C-terminal amino acids is predicted. This observation strongly supports a role for decorin in the pathogenesis of this disorder.

Publication types

  • Case Reports

MeSH terms

  • Corneal Dystrophies, Hereditary / genetics*
  • Corneal Dystrophies, Hereditary / metabolism
  • Corneal Stroma / metabolism*
  • DNA Mutational Analysis
  • Decorin
  • Exons / genetics
  • Extracellular Matrix Proteins / genetics*
  • Family
  • Female
  • Frameshift Mutation*
  • Gene Expression
  • Humans
  • Introns / genetics
  • Male
  • Polymerase Chain Reaction
  • Proteoglycans / genetics*
  • Sequence Deletion

Substances

  • DCN protein, human
  • Decorin
  • Extracellular Matrix Proteins
  • Proteoglycans