Renpenning syndrome in an Indian patient

Am J Med Genet A. 2020 Feb;182(2):293-295. doi: 10.1002/ajmg.a.61457. Epub 2019 Dec 16.

Abstract

Renpenning syndrome is one of the well-characterized causes of X-linked intellectual disability and is associated with microcephaly and various visceral malformations. Face is considered characteristic but the dysmorphism is subtle. Here we report an Indian adult with a very lean habitus, progressive atrophy of the upper back muscles, microcephaly, loss of cervical lordosis, and upper thoracic scoliosis. Using whole-exome sequencing, a hemizygous deletion was identified in PQBP1 that leads to a frameshift and premature termination of translation. The loss of normal curvatures of cervical and upper thoracic spine due to muscular atrophy is a characteristic feature, though it may be age dependent.

Keywords: PQBP1; Renpenning syndrome; X-linked intellectual disability; lean habitus; microcephaly.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Cerebral Palsy / genetics*
  • Cerebral Palsy / pathology
  • DNA-Binding Proteins / genetics*
  • Exome Sequencing
  • Female
  • Genetic Diseases, X-Linked / genetics*
  • Genetic Diseases, X-Linked / pathology
  • Humans
  • Intellectual Disability / genetics*
  • Intellectual Disability / pathology
  • Male
  • Mental Retardation, X-Linked / genetics*
  • Mental Retardation, X-Linked / pathology
  • Microcephaly / diagnosis
  • Microcephaly / genetics
  • Mutation / genetics
  • Pedigree

Substances

  • DNA-Binding Proteins
  • PQBP1 protein, human

Supplementary concepts

  • Renpenning syndrome 1