Bardet-Biedl syndrome presenting with laryngeal web and bifid epiglottis

BMJ Case Rep. 2021 Jan 28;14(1):e236325. doi: 10.1136/bcr-2020-236325.

Abstract

Bardet-Biedl syndrome (BBS) is a rare autosomal recessive ciliopathy characterised by rod-cone dystrophy, obesity, postaxial polydactyly, cognitive impairment, hypogonadism, renal abnormalities, and rarely, laryngeal webs or bifid epiglottis. Most patients present with obesity. Multiple genes are involved in causation of BBS and there is also evidence of triallelic inheritance. We herein report an Asian boy who had weak cry and stridor since birth, and on evaluation was found to have both laryngeal web and bifid epiglottis. Mutation analysis revealed a homozygous variant in BBS10 gene.

Keywords: ear; genetics; nose and throat/otolaryngology; paediatrics.

Publication types

  • Case Reports

MeSH terms

  • Bardet-Biedl Syndrome / complications
  • Bardet-Biedl Syndrome / diagnosis*
  • Bardet-Biedl Syndrome / genetics
  • Bardet-Biedl Syndrome / physiopathology
  • Bronchoscopy
  • Chaperonins / genetics
  • Epiglottis / abnormalities*
  • Fingers / abnormalities
  • Fingers / physiopathology
  • Frameshift Mutation
  • Humans
  • Hypothyroidism / complications
  • Hypothyroidism / diagnosis*
  • Hypothyroidism / drug therapy
  • Infant
  • Larynx / abnormalities*
  • Larynx / surgery
  • Male
  • Pediatric Obesity / physiopathology
  • Polydactyly / physiopathology
  • Thyroxine / therapeutic use
  • Toes / abnormalities
  • Toes / physiopathology

Substances

  • BBS10 protein, human
  • Chaperonins
  • Thyroxine

Supplementary concepts

  • Polydactyly, Postaxial